Qs: why four? Why not lysosome? Gandhi? Klenerman Four disease subtypes of Parkinson’s using patient-derived stem cell models

20230906: Yale, contract, CDA, subtyping papers

이재경 Imaging capability O, serial sampling x, human samples from Columbia university (on-site x), Calvin Lee from Virginia Lee lab. Giasson at univ of Florida completed removed endotoxin,
Endotoxin and aSyn have similar size and neg charge. Removal method: high cathion chromatography and pH optimization, Creiteria? FDA requirement for toxicology? And no TLR4 activation, network with univ of Florida and UAB. RAT model experimece X, but CSF collection from rat was 15-30 uL
Kimitoshi Nakamura's research while affiliated with Kumamoto UniversityLSD
채종희 개인방직봉 02-2072-3622, 비서실 02-2072-3570
[email protected]
Department of Pediatrics, Seoul National University, College of Medicine, Seoul, Korea 110-744
Anthony SchapiraMD -mail: [email protected]
Department of Clinical Neuroscience, Institute of Neurology, UCL, Rowland Hill Street, London NW3 2PF, UK
Fax: +44 20 7472 6829
Tel: +44 20 7830 2012, 020 3448 3015
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  • Sarah Salvage: olimpyic, covid, me GB PD, Alisdair McNeill, Anthony schapira, CSF

Minee Choi

Subtypemechanismstressor
1SNCAX3 mutation
2Human recombinant aSyn oligomer↑ p-aSyn
3MC1-induced mito dysfunctionRotenone (↓ mitophagy?)↑ # of mito-lyso contact spot, ↑ spot to region intensity.
4Mitophagy-induced mito dysfunctionOligomycin and antimycin
  • ~40 Classifiers to predict five classes four disease subtypes and one healthy state — using tabular data based on the nucleus, mitochondria and lysosome features extracted from imaging
    • regarding three key organelles, nucleus (Hoechst3337), mitochondria (TMRM) and lysosome (Lyso)
  • dense neural network
    • overall, the correct label was identified 82% of the time in the five-class model
    • SNCA ×3 = 84%, oligomer = 82%, mitophagy = 81%), (complex 1 = 98%), (control = 69%;
    • subtype 1 (SNCA ×3), five were lysosomal, three were mitochondrial and two were nuclear (Fig. 3e);
    • subtype 2 (oligomer), seven were mitochondrial, two were nuclear and one was lysosomal (Fig. 3f);
    • subtype 3 (complex 1), seven were mitochondrial, two were lysosomal and one was nuclear (Fig. 3g);
    • subtype 4 (mitophagy), six were mitochondrial, two were nuclear and two were lysosomal (Fig. 3h).
  • Convolutional neural network

Kv1.3

A voltage-gated potassium channel

Expression

  • T cells (15, 16) but has since also been identified in B lymphocytes and macrophages, retinal ganglion cells, microglia, and neurons,

STRUCture

  • (Like the other 40 voltage-gated potassium channels found in humans,) Kv1.3 consists of 4 α subunits, each with 6 transmembrane segments (S1-S6) and a voltage sensor in the S4 segment that is responsible for opening the channel in response to membrane depolarization

In PD

Aggregated aSynKv1.3 upregulated & ↑ activityNeuroinflammationNeurodegeneration
EvidenceIn vitroIn primary microglial cultures: ↑ Kv1.3 ({Sarkar, 2020 #1618})
Human postmortem↑ Kv1.3 (frontal cortex) ({Sarkar, 2020 #1618})
Animal models↑ Kv1.3 ({Sarkar, 2020 #1618})({Sarkar, 2020 #1618}, in multiple animal models)
correction({Sarkar, 2020 #1618}, in multiple animal models) (Kv1.3-specific small-molecule) inhibitor PAP-1 → ↓ neuroinflammation↓ neurodegeneration

Pipeline [Muna Tx]

CompoundCompanyModalityRoute of Admin.IndicationsProduct Stage
azatideKv1.3 TherapeuticsSynthetic PeptideOpthalmic, SC, TopicalInclusion Body Myositis / MS
Plaque Psoriasis / Anterior Uveitis
Phase I
Small Molecule Kv1.3 BlockerMetrion BiosciencesSmall MoleculeOralPsoriasis, Neurodegenerative DiseasesPreclinical
44 (peptide)selectIONSynthetic PeptideIV, SCCutaneous T-Cell Lymphoma ArthritisPreclinical
Small Molecule Kv1.3 Blocker4-SCSmall MoleculeOralAutoimmune Disorders / Rheumatoid Arthritis / MSPreclinical

Kyoko Yoshikawa

PD disease area TML,

NDU: BD input

BD → NSTM

  • bd활동아는 것이 PD priority, direction 정하는 데에 도움이 된다.

NSTM →

  • 너희 bd assessment 시 translational input 필요지 않은가?
    • In license 후에 우리가 개발할 때 결국 translational strategy 필요하지 않은가?
  • Eg 어느 회사가 MC1 를 INVOlve 할 수 있지 않은가?
  • 우리 선략이 mito 에서 Parkin PD → Spd 로의 expansion 선략인데, 그 회사가 여기 부합하는가?

AMBER

SP Letter (202102) Confidential review of an asset to revitalize mitochondria for Parkinson’s disease; Kyoko (with ARNU & PhRET)

BD의 Priority 는 무엇? PD? 에서 어떤 Direction?

R&R in your group

  • When I identify external PD opportunity, shall I refer to you (OR Shimojo-san)?

Lee Jonghun

Correlation 안 중요 (sPD에서 stratification 목적으로는) Spd: gene-RNA-Protein/mito BM - UPDRS
4. Identify patients with mito dysfunction
5. 이 군에서 가장 중요한 BM 은 무엇인가?
6. (이 군에서) 이 bm 이 Tx response 있나?
FlowRNA로 어떻게 실제 하나? 환자들 RNA-Seq해서? 여러 gene expression 의 뭉치인데?
stratification DNA
RNA: SN에서의 NEURON에서의 single cell transcriptome 필요. (Only Daria?)
Protein
NDE 밀고, DNA/RNA 무용함을 밀자
Amp-pd data의 작음을 질문
Why SNP
Validation by protein
MJF 에 PARKIN-PD 있나?
DARIA on NLRP3

Lipid category (eight, by Lipid MAPS consortium)

categorySynonymExamplesFunctionIn PD
Fatty acyl(fatty acid)eicosanoids, derived primarily from arachidonic acid and eicosapentaenoic acid, that include prostaglandins, leukotrienes, and thromboxanes. Docosahexaenoic acid
Glycerolipidtriglycerides
Glycerophospholipidphospholipidphosphatidylcholine (also known as PC, GPCho or lecithin), phosphatidylethanolamine (PE or GPEtn) and phosphatidylserineLipid bilayer of cellsGood summary table in …

Uncertain Spans

locationtranscriptionuncertainty
채종희 contact개인방직봉Korean office-name 개인방직봉 reads oddly; may be a stylized contact label such as 개인 직통; preserved verbatim.
Kyoko Yoshikawa bulletbd활동아는 것이Korean phrase bd활동아는 may be bd활동을 아는; preserved verbatim.